Benign intratracheal thyroid tissue is a rare cause of upper airway obstruction. Treatment by radical resection or submucosal excision is advocated in the literature. We report the case of a female patient presenting with stridor due to true thyroid ectopia, which we managed by endoscopic resection. We present our experience of her follow-up 3 years after resection, with no evidence of recurrence and complete patient satisfaction.