Although heart transplantation is a final therapeutic option in pediatric patients with dilated cardiomyopathy (DCMP),the shortage of pediatric heart donors is a major obstacle. In adults with DCMP characterized by cardiac dyssynchrony,cardiac resynchronization therapy (CRT) is known to be an effective treatment option. However, there is alack of evidence on the effectiveness of CRT in infants with DCMP. Several studies have reported improvement inhemodynamics and cardiac performance following CRT in infants with DCMP. Here, we report CRT in an infantwith DCMP during extracorporeal membrane oxygenation with 5 months of follow-up.